Neuralgic amyotrophy is one of the rare neuromuscular diseases characterized by sudden onset of severe pain and sensory deficits in the upper extremities and is followed by muscle weakness and atrophy. The diagnosis is based on the patient’s history and physical findings and is corroborated by electroneuromyography. In this article, we discuss a case of neuralgic amyotrophy with bilateral axillary nerve involvement and its clinical and electrophysiological findings. Turk J Phys Med Rehab 2011;57:107-10.